Pallidal stimulation improves pantothenate kinase-associated neurodegeneration

Ann Neurol. 2005 May;57(5):738-41. doi: 10.1002/ana.20457.

Abstract

Pantothenate kinase-associated neurodegeneration (PKAN) causes a progressive generalized dystonia which remains pharmacologically intractable. We performed bilateral internal globus pallidus stimulation in six patients with genetically confirmed PKAN who obtained a major and long-lasting improvement of their painful spasms, dystonia, and functional autonomy. This study shows the benefits of pallidal DBS for the dystonia of PKAN patients.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adolescent
  • Adult
  • Age of Onset
  • Basal Ganglia / pathology
  • Deep Brain Stimulation*
  • Dystonia / etiology
  • Dystonia / therapy
  • Female
  • Follow-Up Studies
  • Globus Pallidus / physiology*
  • Humans
  • Magnetic Resonance Imaging
  • Male
  • Neurodegenerative Diseases / genetics*
  • Neurodegenerative Diseases / therapy*
  • Phosphotransferases (Alcohol Group Acceptor) / genetics*
  • Spasm / etiology
  • Spasm / therapy
  • Stereotaxic Techniques
  • Treatment Outcome

Substances

  • Phosphotransferases (Alcohol Group Acceptor)
  • pantothenate kinase